A Type 2 Diabetes-Associated Functional Regulatory Variant in a Pancreatic Islet Enhancer at the ADCY5 Locus.
Document Type
Article
Publication Date
9-2017
JAX Source
Diabetes 2017 Sep; 66(9):2521-2530.
Volume
66
Issue
9
First Page
2521
Last Page
2530
ISSN
1939-327X
PMID
28684635
DOI
https://doi.org/10.2337/db17-0464
Grant
R00DK092251
Abstract
Molecular mechanisms remain unknown for most type 2 diabetes genome-wide association study identified loci. Variants associated with type 2 diabetes and fasting glucose levels reside in introns of ADCY5, a gene that encodes adenylate cyclase 5. Adenylate cyclase 5 catalyzes the production of cyclic AMP, which is a second messenger molecule involved in cell signaling and pancreatic β-cell insulin secretion. We demonstrated that type 2 diabetes risk alleles are associated with decreased ADCY5 expression in human islets and examined candidate variants for regulatory function. rs11708067 overlaps a predicted enhancer region in pancreatic islets. The type 2 diabetes risk rs11708067-A allele showed fewer H3K27ac ChIP-seq reads in human islets, lower transcriptional activity in reporter assays in rodent β-cells (rat 832/13 and mouse MIN6), and increased nuclear protein binding compared with the rs11708067-G allele. Homozygous deletion of the orthologous enhancer region in 832/13 cells resulted in a 64% reduction in expression level of Adcy5, but not adjacent gene Sec22a, and a 39% reduction in insulin secretion. Together, these data suggest that rs11708067-A risk allele contributes to type 2 diabetes by disrupting an islet enhancer, which results in reduced ADCY5 expression and impaired insulin secretion. Diabetes 2017 Sep; 66(9):2521-2530.
Recommended Citation
Roman T,
Cannon M,
Vadlamudi S,
Buchkovich M,
Wolford B,
Welch R,
Morken M,
Kwon G,
Varshney A,
Kursawe R,
Wu Y,
Jackson A,
Erdos M,
Kuusisto J,
Laakso M,
Scott L,
Boehnke M,
Collins F,
Parker S,
Stitzel ML,
Mohlke K.
A Type 2 Diabetes-Associated Functional Regulatory Variant in a Pancreatic Islet Enhancer at the ADCY5 Locus. Diabetes 2017 Sep; 66(9):2521-2530.