Document Type

Article

Publication Date

6-25-2024

Keywords

JMG, Animals, Dendritic Cells, Mice, Quantitative Trait Loci, Polymorphism, Single Nucleotide, Mice, Inbred C57BL, Cell Count, Chromosome Mapping, Homeostasis

JAX Source

Cell Rep. 2024;43(6):114296.

ISSN

2211-1247

PMID

38823019

DOI

https://doi.org/10.1016/j.celrep.2024.114296

Abstract

To explore the influence of genetics on homeostatic regulation of dendritic cell (DC) numbers, we present a screen of DCs and their progenitors in lymphoid and non-lymphoid tissues in Collaborative Cross (CC) and Diversity Outbred (DO) mice. We report 30 and 71 loci with logarithm of the odds (LOD) scores >8.18 and ranging from 6.67 to 8.19, respectively. The analysis reveals the highly polygenic and pleiotropic architecture of this complex trait, including many of the previously identified genetic regulators of DC development and maturation. Two SNPs in genes potentially underlying variation in DC homeostasis, a splice variant in Gramd4 (rs235532740) and a missense variant in Orai3 (rs216659754), are confirmed by gene editing using CRISPR-Cas9. Gramd4 is a central regulator of DC homeostasis that impacts the entire DC lineage, and Orai3 regulates cDC2 numbers in tissues. Overall, the data reveal a large number of candidate genes regulating DC homeostasis in vivo.

Creative Commons License

Creative Commons Attribution 4.0 International License
This work is licensed under a Creative Commons Attribution 4.0 International License.

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